Case Report
Copyright ©The Author(s) 2019. Published by Baishideng Publishing Group Inc. All rights reserved.
World J Clin Cases. Nov 26, 2019; 7(22): 3807-3811
Published online Nov 26, 2019. doi: 10.12998/wjcc.v7.i22.3807
Unilateral congenital scrotal agenesis with ipsilateral cryptorchidism: A case report
Yong Fang, Juan Lin, Wen-Wei Wang, Jun Qiu, Yi Xie, Li-Ping Sang, Jia-Cong Mo, Jun-Hang Luo, Jin-Huan Wei
Yong Fang, Wen-Wei Wang, Jun Qiu, Yi Xie, Li-Ping Sang, Jia-Cong Mo, Jun-Hang Luo, Jin-Huan Wei, Department of Urology, First Affiliated Hospital of Sun Yat-sen University, Guangzhou 510080, Guangdong Province, China
Juan Lin, Department of Pediatrics, Third Affiliated Hospital of Sun Yat-sen University, Guangzhou 510630, Guangdong Province, China
Author contributions: Wei JH designed the case report; Lin J, Wang WW, Qiu J, Xie Y, Sang LP, Mo JC, and Luo JH collected the case data; Fang Y wrote the manuscript; Wei JH revised the manuscript. All authors read and approved the final manuscript.
Supported by the National Natural Science Foundation of China, No. 81602219.
Informed consent statement: Written informed consent was obtained from the patient.
Conflict-of-interest statement: The authors declare that they have no conflict of interest.
CARE Checklist (2016) statement: The manuscript was prepared and revised according to the CARE Checklist (2016).
Open-Access: This article is an open-access article which was selected by an in-house editor and fully peer-reviewed by external reviewers. It is distributed in accordance with the Creative Commons Attribution Non Commercial (CC BY-NC 4.0) license, which permits others to distribute, remix, adapt, build upon this work non-commercially, and license their derivative works on different terms, provided the original work is properly cited and the use is non-commercial. See: http://creativecommons.org/licenses/by-nc/4.0/
Corresponding author: Jin-Huan Wei, PhD, Research Fellow, Department of Urology, First Affiliated Hospital of Sun Yat-sen University, No. 58, Zhongshan Er Road, Guangzhou 510080, Guangdong Province, China. wei_jhurol@sina.com
Telephone: +86-20-87755776 Fax: +86-20-87333300
Received: July 27, 2019
Peer-review started: July 27, 2019
First decision: September 9, 2019
Revised: September 19, 2019
Accepted: September 25, 2019
Article in press: September 25, 2019
Published online: November 26, 2019
Processing time: 122 Days and 3.7 Hours
Abstract
BACKGROUND

Congenital scrotal agenesis (CSA) is very rare. There are 11 cases of congenital scrotal agenesis or absence reported in the literature, most of which are bilateral and accompanied by cryptorchidism. Only two cases of which are unilateral scrotal agenesis and not accompanied by cryptorchidism. This is the first reported case of unilateral scrotal agenesis with cryptorchidism and scrotoplasty.

CASE SUMMARY

A 2-year-old boy was admitted to our hospital with left cryptorchidism and ipsilateral CSA. An innovative method was used in the patient where a scrotal skin pedicle from the right part of scrotal skin was transplanted to the left side. At the same time, descent orchiopexy was performed. At the 4-mo follow-up, the left testicle was located in the scrotum and the size and shape were normal.

CONCLUSION

For unilateral CSA with ipsilateral cryptorchidism, contralateral scrotal pedicle transplantation and descent orchiopexy appear to be a successful surgical option.

Keywords: Unilateral congenital scrotal agenesis; Contralateral scrotal pedicle transplantation; Cryptorchidism; Case report

Core tip: Congenital scrotal agenesis is very uncommon. More specially, this is the first reported case of unilateral scrotal agenesis with cryptorchidism. We innovatively transplanted the contralateral scrotal skin flap to the affected side and achieved satisfactory results.