Case Report
Copyright ©The Author(s) 2024. Published by Baishideng Publishing Group Inc. All rights reserved.
World J Hepatol. Dec 27, 2024; 16(12): 1505-1514
Published online Dec 27, 2024. doi: 10.4254/wjh.v16.i12.1505
Multiple intrahepatic artery aneurysms during the treatment for IgG4-related sclerosing cholangitis: A case report
Hotaka Tamura, Yoshinori Ozono, Keisuke Uchida, Naomi Uchiyama, Hiroshi Hatada, Souichiro Ogawa, Hisayoshi Iwakiri, Hiroshi Kawakami
Hotaka Tamura, Yoshinori Ozono, Keisuke Uchida, Naomi Uchiyama, Hiroshi Hatada, Souichiro Ogawa, Hisayoshi Iwakiri, Hiroshi Kawakami, Division of Gastroenterology and Hepatology, Department of Internal Medicine, Faculty of Medicine, University of Miyazaki, Miyazaki 889-1692, Japan
Author contributions: Tamura H and Ozono Y contributed to manuscript writing and editing, and data collection; Kawakami H contributed to manuscript editing and data collection; Uchida K, Uchiyama N, Hatada H, Ogawa S, Iwakiri H, Kawakami H contributed to conceptualization and supervision; all authors have read and approved the final manuscript.
Informed consent statement: Informed written consent was obtained from the patient for publication of this report and any accompanying images.
Conflict-of-interest statement: The authors declare that they have no conflict of interest to disclose.
CARE Checklist (2016) statement: The authors have read the CARE Checklist (2016), and the manuscript was prepared and revised according to the CARE Checklist (2016).
Open-Access: This article is an open-access article that was selected by an in-house editor and fully peer-reviewed by external reviewers. It is distributed in accordance with the Creative Commons Attribution NonCommercial (CC BY-NC 4.0) license, which permits others to distribute, remix, adapt, build upon this work non-commercially, and license their derivative works on different terms, provided the original work is properly cited and the use is non-commercial. See: https://creativecommons.org/Licenses/by-nc/4.0/
Corresponding author: Hiroshi Kawakami, MD, PhD, Professor, Division of Gastroenterology and Hepatology, Department of Internal Medicine, Faculty of Medicine, University of Miyazaki, 5200 Kihara, Kiyotake, Miyazaki 889-1692, Japan. hiropon@med.miyazaki-u.ac.jp
Received: May 21, 2024
Revised: October 1, 2024
Accepted: October 31, 2024
Published online: December 27, 2024
Processing time: 192 Days and 3.1 Hours
Core Tip

Core Tip: Hepatic artery pseudoaneurysm is a disease with poor prognosis due to high rupture and mortality rates. IgG4-related sclerosing cholangitis (IgG4-SC) is a disease caused by an autoimmune mechanism. we report a case of multiple ruptured intrahepatic artery pseudoaneurysms that occurred during the treatment of IgG4-SC. We consider the cause is complex: IgG4-related vasculitis, severe acute obstructive cholangitis and arteriosclerosis. Hepatic artery aneurysms should be considered poor prognostic complications of IgG4-SC.