Case Report
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World J Gastroenterol. Sep 7, 2014; 20(33): 11916-11920
Published online Sep 7, 2014. doi: 10.3748/wjg.v20.i33.11916
Two cases of neuroendocrine carcinoma of the gallbladder
Hao Chen, Yan-Ying Shen, Xing-Zhi Ni
Hao Chen, Xing-Zhi Ni, Department of General Surgery, Ren Ji Hospital, School of Medicine, Shanghai Jiao Tong University, Shanghai 200127, China
Yan-Ying Shen, Department of Pathology, Ren Ji Hospital, School of Medicine, Shanghai Jiao Tong University, Shanghai 200127, China
Author contributions: Chen H, Shen YY and Ni XZ contributed to the manuscript writing and revision; and all authors gave their approval for publishing this version of the manuscript.
Correspondence to: Xing-Zhi Ni, MD, Professor, Department of General Surgery, Ren Ji Hospital, School of Medicine, Shanghai Jiao Tong University, 1630 Dongfang Road, Shanghai 200127, China. niyin92@gmail.com
Telephone: +86-21-68383711 Fax: +86-21-58394262
Received: December 21, 2013
Revised: January 30, 2014
Accepted: March 8, 2014
Published online: September 7, 2014
Processing time: 269 Days and 20.7 Hours
Abstract

Neuroendocrine carcinoma (NEC) of the gallbladder is a rare subtype of gallbladder tumor. Here, we report two cases of NEC in two patients initially suspected to have gallbladder carcinoma. No specific symptoms or abnormal blood test results were observed preoperatively. Abdominal computed tomography scans indicated intraluminal masses in the gallbladder and lymph node enlargement in the hepatic hilum. Radical cholecystectomy and regional lymphadenectomy were performed. The first patient also presented with liver invasion and therefore underwent resection of liver segment IV. A diagnosis of NEC was made upon postoperative pathological examination and immunohistochemical staining according to the WHO Classification of Tumors of the Digestive System (2010). One tumor was identified as poorly differentiated NEC and the other as poorly differentiated mixed adenoneuroendocrine carcinoma. Immunohistochemical staining data from both tumors showed positivity for chromogranin A and synaptophysin. The first patient received 4 cycles of chemotherapy consisting of cisplatin and etoposide. No metastases or recurrence were observed 12 mo following surgery. The second patient refused chemotherapy and presented with tumor recurrence 4 mo after surgery. In conclusion, NEC of the gallbladder is an aggressive tumor and the identification of a standardized optimal treatment still requires further research. Our experience together with published studies suggests that radical surgery and adjuvant chemotherapy may improve the prognosis.

Keywords: Neuroendocrine carcinoma; Tumor; Gallbladder; Chemotherapy; Carcinoid

Core tip: The authors report two cases of neuroendocrine carcinoma of the gallbladder, which is an extremely rare disease. Both patients received radical surgery and showed responses to chemotherapy. The authors discuss possible approaches to improving prognosis including surgery, chemotherapy, radiotherapy and biological targeted therapy in the context of their experience and previously published studies.