Case Report
Copyright ©2008 The WJG Press and Baishideng. All rights reserved.
World J Gastroenterol. May 14, 2008; 14(18): 2924-2927
Published online May 14, 2008. doi: 10.3748/wjg.14.2924
An autopsy case of granulocyte-colony-stimulating-factor-producing extrahepatic bile duct carcinoma
Satoru Matsuyama, Tomonori Shimonishi, Hirofumi Yoshimura, Kensaku Higaki, Kenji Nasu, Mariko Toyooka, Shigehisa Aoki, Keiko Watanabe, Hajime Sugihara
Satoru Matsuyama, Tomonori Shimonishi, Hirofumi Yoshimura, Kenji Nasu, Kensuke Higaki, Department of Surgery, Takagi Hospital, 141-11, Sakemi, Ohkawa-City, Fukuoka 831-0016, Japan
Mariko Toyooka, Keiko Watanabe, Hajime Sugihara, Department of Pathology, Takagi Hospital, 141-11, Sakemi, Ohkawa-City, Fukuoka 831-0016, Japan
Shigehisa Aoki, Department of Pathology and Biodefence, Faculty of Medicine, Saga University, 5-1-1, Nabeshima, Saga-City, Saga 849-8501, Japan
Author contributions: Matsuyama S, Shimonishi T, Yoshimura H, Higaki K and Nasu K treated the patient; Toyooka M, Watanabe K and Sugihara H performed cytological and pathological diagnosis, as well as autopsy, in cooperation with Aoki S.
Correspondence to: Dr. Satoru Matsuyama, Department of Surgery, Takagi Hospital, 141-11, Sakemi, Ohkawa-City, Fukuoka 831-0016, Japan. matsuyama@kouhoukai.org
Telephone: +81-944-870001
Fax: +81-944-87 9310
Received: November 6, 2007
Revised: March 16, 2008
Published online: May 14, 2008
Abstract

A 79-year-old man was referred to this department due to the presence of extrahepatic bile duct carcinoma with a tumor at the left chest wall. The lesion was suspected to be a metastasis of bile duct carcinoma to the left wall, however, computed tomography (CT) revealed no regional lymph node or liver metastases. In addition, cytological and pathological examinations did not show malignancy. At the time of admission, the white blood cell count was 21 460 cells/&mgr;L (neutrophils, 18 240 cells/&mgr;L) and this elevated to 106 040 before death. In addition, serum granulocyte colony-stimulating factor (G-CSF) was elevated. At 28 d after admission, the patient died. An autopsy showed a poorly differentiated adenocarcinoma with sarcomatous change, which had slightly invaded into the pancreas around the bile duct, and was found in the distal bile duct with multiple metastases to the chest wall, lung, kidney, adrenal body, liver, mesentery, vertebra and mediastinal and para-aortic lymph nodes, without locoregional lymph node and liver metastasis. The cancer cells showed positive immunohistochemical staining for anti-G-CSF antibody. This is believed to be the first report of an extrahepatic bile duct carcinoma that produces G-CSF. Since G-CSF-producing carcinoma and sarcomatous change of the biliary tract leads to poor prognosis, early diagnosis and treatment are needed. When infection is ruled out, the G-CSF in serum should be examined. In addition, examinations such as bone scintigraphy and chest CT should also be considered for distant metastasis.

Keywords: Bile duct carcinoma; Granulocyte colony-stimulating factor; Multiple metastases; Autopsy