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For: Jin XL, Wang ZH, Xiao XB, Huang LS, Zhao XY. Blue rubber bleb nevus syndrome: A case report and literature review. World J Gastroenterol 2014; 20(45): 17254-17259 [PMID: 25493043 DOI: 10.3748/wjg.v20.i45.17254]
URL: https://www.wjgnet.com/1007-9327/full/v20/i45/17254.htm
Number Citing Articles
1
Julien Aron, Aymeric Couturier, Leila Sinayoko, Viviane Duedal, Christophe Ridel, Maxime Touzot. An unusual cause of gastrointestinal bleeding in a hemodialysis patient. Hemodialysis International 2018; 22(4) doi: 10.1111/hdi.12657
2
Anwar Khedr, Esraa Elaraby Mahmoud, Noura Attallah, Mikael Mir, Sydney Boike, Ibtisam Rauf, Abbas B Jama, Hisham Mushtaq, Salim Surani, Syed A Khan. Role of octreotide in small bowel bleeding. World Journal of Clinical Cases 2022; 10(26): 9192-9206 doi: 10.12998/wjcc.v10.i26.9192
3
P.H. Aussedat, S. Laroumagne, H. Dutau, P. Astoul. Syndrome de Bean («  blue rubber bleb naevus syndrome  ») avec localisation pleurale. Revue des Maladies Respiratoires 2018; 35(3) doi: 10.1016/j.rmr.2017.06.006
4
Nayera Moftah, May El Samahy, Nadia Abd El Wadood, Monira Waseef. Atlas of Common and Rare Genodermatoses. 2024;  doi: 10.1007/978-3-031-60788-2_7
5
Fabricio Andres Lasso Andrade, Jorge Alejandro Cadena Arteaga, Viviana Lizeth Echeverry Morillo, Ángela María Fajardo Arteaga, Jenny Alexandra Jurado Pantoja, Migdalia Zamirna Zuleny Lasso Anacona, Paula Andrea Nieto Lozano, Daniela Steffany Possos Obando, María Alejandra Palacios Rodríguez, Madelen Alexandra Ortiz Cárdenas, Hermes Albeiro Ortega Díaz, Diana Yulieth Ramírez Anacona, Rodrigo Zanabria Zarmienta. Blue rubber bleb nevus syndrome: Presentation of a case and review of the literature. Radiology Case Reports 2021; 16(8) doi: 10.1016/j.radcr.2021.04.086
6
Hande Kizilocak, Gürcan Dikme, Tiraje Celkan. Sirolimus Experience in Blue Rubber Bleb Nevus Syndrome. Journal of Pediatric Hematology/Oncology 2018; 40(2) doi: 10.1097/MPH.0000000000001070
7
Philippe Attieh, Rim Moubayed, Karam Karam, Ihab l El Hajj, Mahmoud Harb. Blue Rubber Bleb Nevus Syndrome Presenting as Severe Transfusion‐Dependent Anemia in an Elderly Patient: An Unusual Cause of Lower Gastrointestinal Bleeding. Clinical Case Reports 2026; 14(8) doi: 10.1002/ccr3.73253
8
Sara Isoldi, Dalia Belsha, Intan Yeop, Aliye Uc, Noam Zevit, Petar Mamula, Anthony Meneloas Loizides, Merit Tabbers, Don Cameron, Andrew S. Day, Marwa Abu-El-Haija, Voranush Chongsrisawat, Graham Briars, Keith J. Lindley, Jutta Koeglmeier, Neil Shah, John Harper, Samira Batul Syed, Mike Thomson. Diagnosis and management of children with Blue Rubber Bleb Nevus Syndrome: A multi-center case series. Digestive and Liver Disease 2019; 51(11) doi: 10.1016/j.dld.2019.04.020
9
Aysel Ünlüsoy Aksu, Sinan Sari, Ödül Eğritaş Gürkan, Buket Dalgiç. Favorable Response to Sirolimus in a Child With Blue Rubber Bleb Nevus Syndrome in the Gastrointestinal Tract. Journal of Pediatric Hematology/Oncology 2017; 39(2) doi: 10.1097/MPH.0000000000000681
10
Jonas Rauterberg, Julia Schreml, Iliana Tantcheva-Poór. Cutaneous Vascular Malformations in a 53-Year-Old Woman With Neurologic Symptoms. JAMA Dermatology 2023; 159(10) doi: 10.1001/jamadermatol.2023.3216
11
Seema Negi, Anubha Dev, Muthu Sendhil Kumaran. Vascular Tumors Unraveling a Rare Genetic Disorder. Indian Dermatology Online Journal 2025; 16(3) doi: 10.4103/idoj.idoj_1287_24
12
Yuranga Weerakkody, Daniel Bell, Yaïr Glick. Radiopaedia.org. 2016;  doi: 10.53347/rID-44141
13
Fady G. Haddad, Liliane Deeb. A colon in colors!. Clinics and Research in Hepatology and Gastroenterology 2016; 40(5) doi: 10.1016/j.clinre.2016.03.005
14
John Yu Cheng, J. Ben Margines, Neda Abraham, Irena Tsui, David Sarraf. Blue Rubber Bleb Nevus Syndrome and Retinal Cavernous Hemangioma. Retina 2024; 44(12) doi: 10.1097/IAE.0000000000004199
15
Chia-Hua Lin, Bai-Yao Wu, Chih-Tsung Hung, Hong-Wei Gao. Blue rubber bleb nevus syndrome associated with adult-onset cutaneous lesions and spontaneous intracranial hemorrhage: A case report and literature review. Dermatologica Sinica 2018; 36(3) doi: 10.1016/j.dsi.2018.01.002
16
Yohann Pilon, Kashif Khan, Constantine Soulellis. Refractory Blue Rubber Bleb Nevus Syndrome in an Adult: Limitations of Endoscopic Therapy and Sirolimus. ACG Case Reports Journal 2026; 13(7) doi: 10.14309/crj.0000000000002196
17
Muhammad Umer Riaz Gondal, Luke Rovenstine, Fawwad Ansari, Zainab Kiyani, Devi Parvathy Jyothi Ramachandran Nair, Toqeer Khan, Anthony Donato. Navigating a complex case of Mycobacterium xenopi in a patient with blue rubber bleb nevus syndrome. European Journal of Case Reports in Internal Medicine 2024; 11(6) doi: 10.12890/2024_004530
18
Yanqiu Zheng, Amr Shabana, Khaled M. Elsayes, Aws Hamid, Amr Abdelaziz, Christine O. Menias, Akram M. Shaaban, Peter Liu, Ayman H. Gaballah. Cross-Sectional Imaging Evaluation of Vascular Lesions in the Gastrointestinal Tract and Mesentery. Journal of Computer Assisted Tomography 2020; 44(6) doi: 10.1097/RCT.0000000000001107
19
Michael S. Furman, Susan A. Connolly, Stephen D. Brown, Michael J. Callahan. The pediatric stomach — congenital abnormalities. Pediatric Radiology 2021; 51(13) doi: 10.1007/s00247-021-05155-z
20
Fa-Hui Cheng. Blue rubber bleb nevus syndrome with massive gastrointestinal hemorrhage and pulmonary embolism: A case report. World Chinese Journal of Digestology 2023; 31(9) doi: 10.11569/wcjd.v31.i9.385
21
Olga V. Shcherbakova, Alena O. Mager, Artur S. Gabarayev, Saidkhasan M. Bataev. Surgical treatment of an adolescent with Blue rubber bleb nevus syndrome: a case report and review. Russian Journal of Pediatric Surgery, Anesthesia and Intensive Care 2025; 15(3) doi: 10.17816/psaic1928
22
María López-Picazo García, Miriam Alajarín Cervera, Akiko Ono Ono, Víctor Argumánez Tello, Alejandro García Vázquez, Rubén Fernández Nievas, Juan Egea Valenzuela. Blue rubber bleb nevus syndrome as an uncommon cause of gastrointestinal overt bleeding: a diagnostic and therapeutic challenge. Revista Española de Enfermedades Digestivas 2026;  doi: 10.17235/reed.2026.12129/2026
23
Mamoon Ur Rashid, Muzammil Muhammad Khan, Waqas Ullah, Ishtiaq Hussain, Abu Hurairah. Blue rubber bleb nevus: a rare cause of GI bleeding—review of management. BMJ Case Reports 2019; 12(12) doi: 10.1136/bcr-2019-231561
24
Felipe S. Barros, Victor Hugo R. Marussi, Lázaro L.F. Amaral, Antônio José da Rocha, Christiane M.S. Campos, Leonardo F. Freitas, Thierry A.G.M. Huisman, Bruno P. Soares. The Rare Neurocutaneous Disorders. Topics in Magnetic Resonance Imaging 2018; 27(6) doi: 10.1097/RMR.0000000000000185
25
Nazila Heidari, SeyedAyin Hosseini. Genetic Syndromes. 2023;  doi: 10.1007/978-3-319-66816-1_1084-1
26
Jo Cooke-Barber, Roshni Dasgupta. Management of visceral vascular anomalies. Seminars in Pediatric Surgery 2020; 29(5) doi: 10.1016/j.sempedsurg.2020.150977
27
Shufen Wang, Sijian Wen, Jiarong Liang, Hui Lui, Xinyu Zhang. Sclerotherapy in a case of multiple glomuvenous malformation. Chinese Journal of Plastic and Reconstructive Surgery 2024; 6(2) doi: 10.1016/j.cjprs.2024.05.001
28
Han-Bo Li, Jing-Fang Lv, Ning Lu, Zong-Shun Lv. Mechanical intestinal obstruction due to isolated diffuse venous malformations in the gastrointestinal tract: A case report and review of literature. World Journal of Clinical Cases 2020; 8(1): 157-167 doi: 10.12998/wjcc.v8.i1.157
29
Joyce Teng, Jeff Martini, Michael Kelly, Megha Tollefson, Alexander Greer. Sirolimus for Venous Malformations: A Systematic Review of Efficacy and Safety. Lymphatic Research and Biology 2025; 23(6) doi: 10.1177/15578585251377562
30
B. Zhang, L. Li, N. Zhang, M. Zhao, Y. Liu, L. Wei, L. Ma, Z. Xu. Efficacy and safety of sirolimus in the treatment of blue rubber bleb naevus syndrome in paediatric patients. Clinical and Experimental Dermatology 2020; 45(1) doi: 10.1111/ced.14003
31
Fatimah Mat Johar, Wan Azman Wan Sulaiman, Arman Zaharil Mat Saad, Normala Basiron, Nik Amin Sahid. Blue rubber bleb nevus syndrome in a Malay girl. International Journal of Surgery Case Reports 2020; 72(C) doi: 10.1016/j.ijscr.2020.05.036
32
Mengqi Pi, Lei Zhao, Weiyang Xu, Miao Xu, Yu Ding. Case report: Blue rubber bleb nevus syndrome with Kasabach-Merritt phenomenon in a neonate. Frontiers in Pediatrics 2023; 11 doi: 10.3389/fped.2023.1131094
33
Caitlin M. Peterman, Patricia S. Todd, Anna P. Lillis, Steven J. Fishman, Marilyn G. Liang. Internal venous anomalies in patients with a genital venous malformation. Pediatric Dermatology 2018; 35(1) doi: 10.1111/pde.13358
34
Ke-Ling Wang, Shu-Fang Ma, Ling-Yu Pang, Meng-Na Zhang, Lin-Yan Hu, Meng-Jia Liu, Li-Ping Zou. Sirolimus alternative to blood transfusion as a life saver in blue rubber bleb nevus syndrome. Medicine 2018; 97(8) doi: 10.1097/MD.0000000000009453
35
Mian Wang, Hui Wang, Bingye Liao, Guiyan Peng, Guangqi Chang. Treatment strategies for inferior vena cava aneurysms. Journal of Vascular Surgery: Venous and Lymphatic Disorders 2021; 9(6) doi: 10.1016/j.jvsv.2021.03.017
36
Irene Pradelle, Marta Helenowski, Lauren M. Woertz, Lorenzo Gitto. Fatal tracheostomy-site hemorrhage in blue rubber bleb nevus syndrome: case report and literature review. Forensic Science, Medicine and Pathology 2026;  doi: 10.1007/s12024-026-01172-2
37
Yeo Min Cho, Christopher Steen, Justin James. Blue rubber bleb nevus syndrome: a rare cause of abdominal pain. ANZ Journal of Surgery 2020; 90(4) doi: 10.1111/ans.15247
38
Niraj Dhinoja, Shubhangi Hirma, Rita Vipul Vora. Dermoscopic Features of Blue Rubber Bleb Nevus Syndrome. Indian Journal of Paediatric Dermatology 2023; 24(4) doi: 10.4103/ijpd.ijpd_22_23
39
Philip R. Cohen. The color of skin: blue diseases of the skin, nails, and mucosa. Clinics in Dermatology 2019; 37(5) doi: 10.1016/j.clindermatol.2019.07.006
40
Martin Hult, Halla Halldorsdottir, Ylva Vladic Stjernholm, Anette Hein, Henrik Jörnvall. Blue Rubber Bleb Nevus Syndrome in the Obstetric Patient: A Case Report of Anesthetic Implications and Management. A&A Practice 2021; 15(8) doi: 10.1213/XAA.0000000000001517
41
Aditya Goud, Abdelhai Abdelqader, Jamie Walters, Stephen Selinger. Blue rubber bleb nevus syndrome: a rare presentation of late-onset anemia and lower gastrointestinal bleeding without cutaneous manifestations. Journal of Community Hospital Internal Medicine Perspectives 2016; 6(1) doi: 10.3402/jchimp.v6.29966
42
Michał Ciebiera, Anna Kucińska-Chahwan, Włodzimierz Piwowar, Aneta Kalcowska, Tomasz Roszkowski, Grzegorz Jakiel. Blue Rubber Bleb Nevus Syndrome Diagnosed Prenatally as an Epignathus. Journal of Craniofacial Surgery 2016; 27(8) doi: 10.1097/SCS.0000000000003069
43
Benjamin Wipper, Hanna Blaney, Robert Giraneza, Prosper Ingabire, Vincent Dusabejambo, Udit Asija, Erik C von Rosenvinge. Rwandan man with a case of the blues. Frontline Gastroenterology 2024; 15(5) doi: 10.1136/flgastro-2024-102722
44
Kumi Nitta, Akira Matsui, Akihiro Araki, Daisuke Kikuchi, Shu Hoteya. Clipping with double-balloon endoscopy for small intestinal venous malformations in a patient with blue rubber bleb nevus syndrome. Clinical Journal of Gastroenterology 2022; 15(5) doi: 10.1007/s12328-022-01670-0
45
Qaisar Ali Khan, Christopher Farkouh, Arooba Khan, Zahir Uddin, Parsa Abdi, Michelle R Anthony, Faiza Amatul Hadi, Eyan Khan, Sara Pervez. Blue Rubber Bleb Nevus Syndrome Presenting as Anemia, Hemorrhage, and Hemangiomas: A Rare Case Report. Clinical Medicine Insights: Case Reports 2023; 16 doi: 10.1177/11795476231173503
46
Martin Bell Lybecker, Marek Stawowy, Niels Clausen. Blue rubber bleb naevus syndrome: a rare cause of chronic occult blood loss and iron deficiency anaemia. BMJ Case Reports 2016; 2016 doi: 10.1136/bcr-2016-216963
47
F M Salinas Nuñez, S Redondo Evangelista, M I Higuera Fernandez, C Golmayo Flethes, A Santos Rodríguez, L Gonzalez Sanchez Ocaña, C Trueba Collado, R Benabdallah, A Castellano Lopez, S Tabernero Da Veiga. Multiple Vascular Lesions in the Gastrointestinal Tract: A Case of Blue Bleb Venous Nevus Syndrome. ESGE Days 2025 2025; 57 doi: 10.1055/s-0045-1805962
48
Alessandro Rimondi, Andrea Sorge, Alberto Murino, Nicoletta Nandi, Lucia Scaramella, Maurizio Vecchi, Gian Eugenio Tontini, Luca Elli. Treatment options for gastrointestinal bleeding blue rubber bleb nevus syndrome: Systematic review. Digestive Endoscopy 2024; 36(2) doi: 10.1111/den.14564
49
Pierre Ellul, John Schembri. Vascular Anomalies and Inflammatory Bowel Disease. Journal of Crohn's and Colitis 2016; 10(1) doi: 10.1093/ecco-jcc/jjv163
50
Pedro Ezomo-Gervilla, Israel Perez-Lopez, Pablo Velasco-Amador, Ricardo Ruiz-Villaverde. Cuando las lesiones cutáneas revelan lo oculto: síndrome del nevo azul en tetina de goma. Piel 2026;  doi: 10.1016/j.piel.2026.03.011
51
Enrique Pérez-Cuadrado Martínez, Enrique Pérez-Cuadrado Robles. Advanced therapy by device-assisted enteroscopy. Revista Española de Enfermedades Digestivas 2020; 112 doi: 10.17235/reed.2020.6971/2020
52
G. Blanco-Velasco, R. Zamarripa-Mottú, O.M. Solórzano-Pineda, E. Murcio-Pérez, O.V. Hernández-Mondragón. Síndrome de blue rubber-bleb nevus en pacientes geriátricos. Revista de Gastroenterología de México 2020; 85(2) doi: 10.1016/j.rgmx.2019.03.004
53
Yuchen Shen, Lixin Su, Xindong Fan, Deming Wang. Images in Vascular Medicine: Clinical and radiological features of Maffucci syndrome. Vascular Medicine 2022; 27(5) doi: 10.1177/1358863X221101654
54
Hiroyuki FUKANO, Masaomi SUZUKI, Tetsuyosi TAKAYAMA, Hiroshi ASANO, Nozomi SHINOZUKA, Takaya ICHIMURA. Small Intestinal Bleeding Secondary to Blue Rubber Bleb Nevus Syndrome without Skin Manifestations—A Case Report—. Nihon Rinsho Geka Gakkai Zasshi (Journal of Japan Surgical Association) 2021; 82(6) doi: 10.3919/jjsa.82.1115
55
Ralph Salloum, Courtney E. Fox, Carlos R. Alvarez‐Allende, Adrienne M. Hammill, Roshni Dasgupta, Belinda H. Dickie, Paula Mobberley‐Schuman, Mary Sue Wentzel, Carol Chute, Ajay Kaul, Manish Patel, Arnold C. Merrow, Anita Gupta, John R. Whitworth, Denise M. Adams. Response of Blue Rubber Bleb Nevus Syndrome to Sirolimus Treatment. Pediatric Blood & Cancer 2016; 63(11) doi: 10.1002/pbc.26049
56
Zeming Hu, Xuan Lin, Jianing Zhong, Qingfang He, Qin Peng, Jianbo Xiao, Bin Chen, Jianhong Zhang. Blue rubber bleb nevus syndrome with the complication of intussusception. Medicine 2020; 99(28) doi: 10.1097/MD.0000000000021199
57
Kyung Ho Lee, Joo Ho Jeong, Chul Jong Park, Yoon-Seob Kim. Multiple Blue-Coloured Nodules on the Whole Body. Indian Journal of Dermatology 2026; 71(2) doi: 10.4103/ijd.ijd_383_24
58
Anthony S Larson, Waleed Brinjikji, Katelyn R Anderson, Megha Tollefson, V. Michelle Silvera, Julie B. Guerin. Imaging of benign cervicofacial vascular anomalies and associated syndromes. Interventional Neuroradiology 2022; 28(3) doi: 10.1177/15910199211034989
59
Anasuya Guha, Petr Schalek, Martin Chovanec. Syndromes that predispose to epistaxis. European Archives of Oto-Rhino-Laryngology 2019; 276(4) doi: 10.1007/s00405-019-05310-1
60
Maria Fernanda Tibaduiza Garcia, Caren Ton, Marcos S. Munera, Maribel Plaza Tenorio. Síndrome de nevus azules cauchosos: reporte de un caso familiar. Revista de la Asociación Colombiana de Dermatología y Cirugía Dermatológica 2022; 30(3) doi: 10.29176/2590843X.1649
61
García Anwár, Paredes-Aragón Elma, Jorge-de Saráchaga Adib, Meyer-Nava Ilse, Gutiérrez-Romero Alonso, Salinas Lara Ciltlaltepelt, Novelo Soto Alma, Vega Memije Maria Elisa, Arauz Antonio. Blue Rubber Bleb Nevus Syndrome With Multiple Cavernoma-Like Lesions on MRI: A Familial Case Report and Literature Review. Frontiers in Neurology 2020; 11 doi: 10.3389/fneur.2020.00176
62
Robert A. Norman, Trupal Patel, Tam H. Nguyen. Geriatric Gastroenterology. 2020;  doi: 10.1007/978-3-319-90761-1_90-1
63
Naiem Nassiri, Lauren A. Huntress. Textbook of Catheter-Based Cardiovascular Interventions. 2018;  doi: 10.1007/978-3-319-55994-0_86
64
Mariko Aizawa, Satoshi Ishihara, Takeshi Yokoyama. Anesthetic considerations for blue rubber bleb nevus syndrome: a case report. JA Clinical Reports 2019; 5(1) doi: 10.1186/s40981-019-0304-4
65
Xin-Ying Tang, Chao-Hui He, Zhuan Liao. Successful endoscopic diagnosis and treatment of blue rubber bleb nevus syndrome. Endoscopy 2021; 53(04) doi: 10.1055/a-1202-0716
66
Jennifer T. Duong, Amy Geddis, Katie Carlberg, Erin Rudzinski, Mary Len, Hengqi B. Zheng. Sirolimus for management of GI bleeding in blue rubber bleb nevus syndrome: A case series. Pediatric Blood & Cancer 2022; 69(11) doi: 10.1002/pbc.29970
67
Aditya Mithanthaya, Ali Galalah Mostafa Ismail, Niroshan Muwanwella, Kannan Venugopal. Blue rubber bleb nevus syndrome in a patient on anticoagulation: a management dilemma. BMJ Case Reports 2023; 16(11) doi: 10.1136/bcr-2023-256702
68
Bin Zhang, Lin Ma. Updated classification and therapy of vascular malformations in pediatric patients. Pediatric Investigation 2018; 2(2) doi: 10.1002/ped4.12043
69
Uzoamaka T. Ukoha, Travis Vandergriff, Jonathan Cheng, Donald A. Glass. Multiple Tumors on the Extremities: Answer. The American Journal of Dermatopathology 2018; 40(8) doi: 10.1097/DAD.0000000000000851
70
Hideaki Nakajima, Hiroshi Nouso, Naoto Urushihara, Koji Fukumoto, Masaya Yamoto, Hiromu Miyake, Akinori Sekioka, Akiyoshi Nomura, Yutaka Yamada. Blue Rubber Bleb Nevus Syndrome with Long-Term Follow-Up: A Case Report and Review of the Literature. Case Reports in Gastrointestinal Medicine 2018; 2018 doi: 10.1155/2018/8087659
71
Aymeric Becq, Annouk Bisdorff, Maria Elena Riccioni, Sophie Blaise, Stéphanie Mallet, Ervin Toth, Annabel Maruani, Edward Despott, Christine Labreze, Pablo Cortegoso Valdivia, Emmanuele Rondonotti, Cristina Carrretero Ribón, Laetitia Goffinet, Elise Coffin, Bruno Rosa, Cynthia Medlij, Jean-Christophe Saurin, Xavier Dray. Blue rubber bleb nevus syndrome: A European multicenter cohort study. Digestive and Liver Disease 2025; 57(2) doi: 10.1016/j.dld.2024.10.001
72
Jerzy Lasota. Modern Soft Tissue Pathology. 2016;  doi: 10.1017/9781107707504.006
73
Robert A. Norman, Trupal Patel, Tam H. Nguyen. Geriatric Gastroenterology. 2021;  doi: 10.1007/978-3-030-30192-7_90
74
Arghya Samanta, Ujjal Poddar, Moinak Sen Sarma, Anshu Srivastava, Surender Kumar Yachha, Samir Mohindra. Endoscopic Band Ligation in Blue Rubber Bleb Nevus Syndrome: A Report of Two Children. JPGN Reports 2023; 4(4) doi: 10.1097/PG9.0000000000000344
75
F. Topaloglu Demir, F. Deniz, A. Mesrur Halefoglu, I. Kivanc Altunay, K. Esen Salman. Unilateral blue rubber bleb naevus syndrome with Chiari malformation. Clinical and Experimental Dermatology 2017; 42(2) doi: 10.1111/ced.13012
76
Jian-Xun Ma, You-Chen Xia, Li-Ping Zou, Heng-Ju Lin, Xu Chang, Li-Ying Liu, Joy Roechelle A. Toledo. Sirolimus as a promising drug therapy for blue rubber bleb nevus syndrome: Two-case report. SAGE Open Medical Case Reports 2022; 10 doi: 10.1177/2050313X221097755
77
Yu-Jui Chang, Jih-Yang Ko, Jiunn-Ming Sheen, Ka-Kit Siu. Treatment of sirolimus in the pathological femoral fracture related to blue rubber bleb nevus syndrome: A case report. Medicine 2022; 101(30) doi: 10.1097/MD.0000000000029679
78
L. A. Hachatryan, I. S. Kletskaya, E. V. Orekhova. Syndromе associated with multiple venous malformations (Bean syndrome). Pediatric Hematology/Oncology and Immunopathology 2019; 18(3) doi: 10.24287/1726-1708-2019-18-3-78-87
79
Stephanie Bowe, Veronika Dvorakova. Syndromic vascular anomalies: A challenge. La Presse Médicale 2025; 54(3) doi: 10.1016/j.lpm.2025.104294
80
Arnes Rešić, Ana Močić Pavić, Ante Čizmić, Ines Potočnjak. Blue rubber bleb nevus syndrome: A rare cause of gastrointestinal bleeding and vascular anomaly in children. Vascular Medicine 2018; 23(1) doi: 10.1177/1358863X17735596
81
Blue Rubber Bleb Nevus Syndrome: A Case Report of an Uncommon Vascular Malformation. Indian Journal of Vascular and Endovascular Surgery 2025; 12(4) doi: 10.4103/ijves.ijves_54_25
82
Amr Abdelhamid AbouZeid, Shaimaa AbdelSattar Mohammad, Iman Ahmed Ragab. Atlas of Pediatric Vascular Anomalies. 2026;  doi: 10.1007/978-3-032-30866-5_16
83
Carlos Augusto Metidieri Menegozzo, Fernando da Costa Ferreira Novo, Newton Djin Mori, Celso de Oliveira Bernini, Edivaldo Massazo Utiyama. Postoperative disseminated intravascular coagulation in a pregnant patient with Blue Rubber Bleb Nevus Syndrome presenting with acute intestinal obstruction: Case report and literature review. International Journal of Surgery Case Reports 2017; 39 doi: 10.1016/j.ijscr.2017.08.026
84
Harpreet S. Gill, Paul Beinhoff, Sarah Grond, Mohan S. Dhariwal, Pinky Jha, Yoshifumi Nakayama. Atypical Blue Rubber Bleb Nevus in an African-American Male. Case Reports in Gastrointestinal Medicine 2021; 2021 doi: 10.1155/2021/9992111
85
秋月 王. Blue Rubber Blister Nevus Syndrome: A Case Report and Literature Review. Advances in Clinical Medicine 2021; 11(03) doi: 10.12677/ACM.2021.113195
86
Rui Mendo, Rita Barosa, Pedro Figueiredo, Cristina Chagas. An Unusual Cause of Anemia: Throwing the Cat among the Pigeons. GE - Portuguese Journal of Gastroenterology 2022; 29(1) doi: 10.1159/000514010
87
Jian-Hua Zhai, Shi-Xin Li, Ge Jin, Yuan-Yuan Zhang, Wei-Long Zhong, Yan-Fen Chai, Bang-Mao Wang. Blue rubber bleb nevus syndrome complicated with disseminated intravascular coagulation and intestinal obstruction: A case report. World Journal of Clinical Cases 2022; 10(32): 11929-11935 doi: 10.12998/wjcc.v10.i32.11929
88
Xue Tang, Ju Gao, Xue Yang, Xia Guo. A 10-year delayed diagnosis of blue rubber bleb nevus syndrome characterized by refractory iron-deficiency anemia. Medicine 2018; 97(22) doi: 10.1097/MD.0000000000010873
89
N. Litaiem, A. Chabbouh, F. Zeglaoui. Etiologies of blue lips: A review. Annales de Dermatologie et de Vénéréologie 2025; 152(1) doi: 10.1016/j.annder.2024.103334
90
Kirill Marakhouski, Elena Sharafanovich, Uladzislau Kolbik, Aleh Sautin, Katsiaryna Nikalayeva, Aleh Pataleta, Kiryl Sanfirau, Aliaksandr Svirsky. Endoscopic treatment of blue rubber bleb nevus syndrome in a 4-year-old girl with long-term follow-up: A case report. World Journal of Gastrointestinal Endoscopy 2021; 13(3): 90-96 doi: 10.4253/wjge.v13.i3.90
91
Ivone Melo Valad�o, Maria Guadalupe Benites. An unusual cause of anaemia: Bean syndrome. Revista Española de Enfermedades Digestivas 2021;  doi: 10.17235/reed.2021.8522/2021
92
Abhay Goyal, Sushruta Kathuria, Anshuman Dash, Shyam S. Meena, Niti Khunger. Oral sirolimus in blue rubber bleb naevus syndrome: Evidence of safety, efficacy, and improved quality of life. Indian Journal of Dermatology, Venereology and Leprology 2025; 0 doi: 10.25259/IJDVL_248_2025
93
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